Maintenance Notice

Due to necessary scheduled maintenance, the JMIR Publications website will be unavailable from Wednesday, July 01, 2020 at 8:00 PM to 10:00 PM EST. We apologize in advance for any inconvenience this may cause you.

Who will be affected?

Accepted for/Published in: JMIR Bioinformatics and Biotechnology

Date Submitted: Sep 30, 2021
Date Accepted: Apr 27, 2022

The final, peer-reviewed published version of this preprint can be found here:

Identification of a Novel c.3080delC JAG1 Gene Mutation Associated With Alagille Syndrome: Whole Exome Sequencing

Panwar DD, Singh DKG, Mathur MS, Prasad MB, Joshi MA, Lal DV, Thatai A

Identification of a Novel c.3080delC JAG1 Gene Mutation Associated With Alagille Syndrome: Whole Exome Sequencing

JMIR Bioinform Biotech 2022;3(1):e33946

DOI: 10.2196/33946

PMID: 27683065

PMCID: 5041145

Warning: This is an author submission that is not peer-reviewed or edited. Preprints - unless they show as "accepted" - should not be relied on to guide clinical practice or health-related behavior and should not be reported in news media as established information.

Identification of a novel c.3080delC JAG1 gene mutation associated with Alagille syndrome by whole-exome sequencing

  • Dr. Deepak Panwar; 
  • Dr. Kumar Gautam Singh; 
  • Ms. Shruti Mathur; 
  • Mr. Bhagwati Prasad; 
  • Ms. Anita Joshi; 
  • Dr. Vandana Lal; 
  • Atul Thatai

ABSTRACT

Background:

Alagille syndrome is an autosomal dominant disorder associated with variable clinical phenotypic features including cholestasis, congenital heart defects, vertebral defects, and dysmorphic facies.

Objective:

Whole-exome sequencing (WES) has become technically feasible due to the recent advances in next-generation sequencing technologies, therefore offering new opportunities for mutations/genes identification.

Methods:

Next-generation sequencing (NGS) - Whole-exome sequencing was used to identify pathogenic variants of the proband. In this paper, we have uncovered a novel JAG1 mutation associated with Alagille syndrome in a 5 years old girl presented with conjugated hyperbilirubinemia and infantile cholestasis.

Results:

The exome sequencing analysis revealed the presence of a novel JAG1 heterozygous c.3080delC variant in exon 25. The detected mutation determines a stop codon (p.P1027RfsTer9) in the gene sequence, encoding a truncated protein. Our exome observations were confirmed through Sanger sequencing as well.

Conclusions:

Here, we report a case of a patient diagnosed with Alagille syndrome, and our finding emphasis the detection of novel JAG1 mutation associated with Alagille syndrome variants thereby, establishing the genetic diagnosis of the disease. Clinical Trial: N/A


 Citation

Please cite as:

Panwar DD, Singh DKG, Mathur MS, Prasad MB, Joshi MA, Lal DV, Thatai A

Identification of a Novel c.3080delC JAG1 Gene Mutation Associated With Alagille Syndrome: Whole Exome Sequencing

JMIR Bioinform Biotech 2022;3(1):e33946

DOI: 10.2196/33946

PMID: 27683065

PMCID: 5041145

Download PDF


Request queued. Please wait while the file is being generated. It may take some time.

© The authors. All rights reserved. This is a privileged document currently under peer-review/community review (or an accepted/rejected manuscript). Authors have provided JMIR Publications with an exclusive license to publish this preprint on it's website for review and ahead-of-print citation purposes only. While the final peer-reviewed paper may be licensed under a cc-by license on publication, at this stage authors and publisher expressively prohibit redistribution of this draft paper other than for review purposes.