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Currently submitted to: JMIR Preprints

Date Submitted: Dec 28, 2022

Warning: This is an author submission that is not peer-reviewed or edited. Preprints - unless they show as "accepted" - should not be relied on to guide clinical practice or health-related behavior and should not be reported in news media as established information.

Pre-existing neutralizing antibodies against different adeno-associated virus serotypes in humans and large animal models for gene therapy

  • Divya Ail; 
  • Deniz Dalkara

ABSTRACT

Gene therapy is a potential cure for several inherited retinal dystrophies and adeno-associated virus (AAV) has emerged as a vector of choice for therapeutic gene delivery to the retina. However, prior exposure to AAVs can cause a humoral immune response resulting in the presence of antibodies in the serum, which can subsequently interfere with the AAV-mediated gene therapy. The antibodies bind specifically to a serotype, but often display broad cross-reactivity. A subset of these antibodies called Neutralizing Antibodies (NABs) can render the AAV inactive thereby reducing the efficacy of the therapy. The pre-existing NAB levels against different serotypes vary by species, and these variations need to be considered while designing studies. Since large animals often serve as preclinical models to test gene therapies, in this review we compile studies reporting pre-existing NABs against commonly used AAV serotypes in humans and large animal models and discuss strategies to deal with NABs.


 Citation

Please cite as:

Ail D, Dalkara D

Pre-existing neutralizing antibodies against different adeno-associated virus serotypes in humans and large animal models for gene therapy

JMIR Preprints. 28/12/2022:45386

DOI: 10.2196/preprints.45386

URL: https://preprints.jmir.org/preprint/45386

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